Case report of a patient with osteopoikilosis (original) (raw)

Abstract

Osteopoikilosis (OPK) is a benign osteosclerotic dysplasia of unknown origin, which is an inherited autosomal disorder. Males and females are equally affected. It is usually asymptomatic and may only be recognized on radiological examination. In this study we report a 33-year-old woman with fibromyalgia who suffers from back and leg pain and was diagnosed OPK by radiologically and review literature.

Access this article

Log in via an institution

Subscribe and save

Buy Now

Price excludes VAT (USA)
Tax calculation will be finalised during checkout.

Instant access to the full article PDF.

References

  1. Benli IT, Akalin S, Boysan E, Mumcu EF et al (1992) Epidemiological, clinical and radiological aspects of osteopoikilosis. J Boint Surg 74:504–506
    CAS Google Scholar
  2. Günal I, Seber S, Başaran N et al (1993) Dacryocystitis associated with osteopoikilosis. Clin Genet 44:211–213
    Article PubMed Google Scholar
  3. Walker GF (1964) Mixed sclerosing bone dystrophies. Two case reports. J Bone Joint Surg 46:654–552
    Google Scholar
  4. Ostrowski DM, Gilula LA (1992) Mixed sclerosing bone dystrophy presenting with upper extremity deformities. A case report and review of the literature. J Hand Surg 17:108–112
    CAS Google Scholar
  5. Reznick D, Niwayama G (1988) Enostosis, hyperostosis and periostitis. In: Reznick D, Niwayama G (eds) Diagnosis of bone and joint disorders. W.B Saunders Company, Philadelphia, pp 4084–4088
    Google Scholar
  6. Goldenberg DL (2003) Fibromyalgia and related syndromes. In: Textbook of rheumatology, 3rd edn. Mosby, Philadelphia, pp 701–710
    Google Scholar
  7. Chigara M, Kato K, Mashio K, Shinozaki T (1991) Symmetry of bone lesions in osteopoikilosis: a report of four cases. Acta Orthop Scand 62:495–496
    Google Scholar
  8. Green AE, Ellswood WH, Collins JR (1962) Melorheostosis and osteopoikilosis with a review of the literature. AJR 86:1096–1110
    Google Scholar
  9. Lagier R, Mbakop A, Bigler A (1984) Osteopoikilosis: a radiological and pathological study. Skeletal Radiol 11(3):161–168
    Article PubMed CAS Google Scholar
  10. Mindell ER, Northup CS, Gouglass HO Jr (1978) Osteosarcoma associated with osteopoikilosis. Case report. J Bone Joint Surg (Am) 60:406–408
    CAS Google Scholar
  11. Vanhoenacker FM, De Beuckeleer LH, Van Hul W et al (2000) Sclerosing bone dysplasias: genetic and radioclinical features. Eur Radiol 10:1423–1433
    Article PubMed CAS Google Scholar
  12. Resnick D (1996) Enostosis, hyperostosis and periostitis. In: Bone and joint imaging. Saunders, Philadelphia, pp 1213–1214
    Google Scholar
  13. Woodrow SL, Pope FM, Handfield-Jones SE (2001) The Buschkle-Ollendorf syndrome presenting as familial elastic tissue naive. Br J Dermatol 144:890–893
    Article PubMed CAS Google Scholar
  14. Bicer A, Tursen U, Ozer C, Kaya TI et al (2002) Coexistence of osteopoikilosis and discoid lupus erythematosus: a case report. Clin Rheumatol 21:405–407
    Article PubMed CAS Google Scholar
  15. Verbov J (1977) Bushkle-Ollendorff syndrome. (Disseminated dermatofibrosis with osteopoikilosis). Br J Dermatol 96:87–90
    Article PubMed CAS Google Scholar
  16. Duke-Elder S (1974) System of ophthalmology, vol 12, 1st edn. Henry Kimpton Publishers, London
  17. Weisz GM (1982) Lumbar spinal canal stenosis in osteopoikilosis. Clin Orthop 166:89–92
    PubMed Google Scholar
  18. Gunal I, Kıter E (2003) Disorders associated with osteopoikilosis. Acta Orthop Scand 74(4):497–499
    Article PubMed Google Scholar
  19. Mungovan JA, Tung GA, Lambiase RE et al (1994) Tc-99m MDP uptake in osteopoikilosis. Clin Nucl Med 19(1):6–8
    Article PubMed CAS Google Scholar
  20. Havitcioğlu H, Günal I, Göcen S (1998) Synovial chondromatosis associated with osteopoikilosis; a case report. Acta Orthop Scand 69:649–650
    Article PubMed Google Scholar
  21. Middleton GD, McFarlin JE, Lipsky PE (1994) The prevalence and clinic impact of in fibromyalgia in systemic lupus erythematosus. Arthritis Rheum 37:1181–1188
    Article PubMed CAS Google Scholar
  22. Bonafede RP, Downey DC, Bennett RM (1995) An association of fibromyalgia with primary Sjögren’s syndrome: a prospective study of 72 patients. J Rheumatol 22:133–136
    PubMed CAS Google Scholar

Download references

Author information

Authors and Affiliations

  1. Medical Faculty, Physical Therapy & Rehabilitation, Karadeniz Technical University, Trabzon, Turkey
    Münevver Serdaroğlu, Erhan Çapkın, Faik Üçüncü & Mehmet Tosun

Authors

  1. Münevver Serdaroğlu
    You can also search for this author inPubMed Google Scholar
  2. Erhan Çapkın
    You can also search for this author inPubMed Google Scholar
  3. Faik Üçüncü
    You can also search for this author inPubMed Google Scholar
  4. Mehmet Tosun
    You can also search for this author inPubMed Google Scholar

Corresponding author

Correspondence toMünevver Serdaroğlu.

Rights and permissions

About this article

Cite this article

Serdaroğlu, M., Çapkın, E., Üçüncü, F. et al. Case report of a patient with osteopoikilosis.Rheumatol Int 27, 683–686 (2007). https://doi.org/10.1007/s00296-006-0262-9

Download citation

Keywords