Suppression of basal autophagy in neural cells causes neurodegenerative disease in mice - PubMed (original) (raw)
. 2006 Jun 15;441(7095):885-9.
doi: 10.1038/nature04724. Epub 2006 Apr 19.
Affiliations
- PMID: 16625204
- DOI: 10.1038/nature04724
Suppression of basal autophagy in neural cells causes neurodegenerative disease in mice
Taichi Hara et al. Nature. 2006.
Abstract
Autophagy is an intracellular bulk degradation process through which a portion of the cytoplasm is delivered to lysosomes to be degraded. Although the primary role of autophagy in many organisms is in adaptation to starvation, autophagy is also thought to be important for normal turnover of cytoplasmic contents, particularly in quiescent cells such as neurons. Autophagy may have a protective role against the development of a number of neurodegenerative diseases. Here we report that loss of autophagy causes neurodegeneration even in the absence of any disease-associated mutant proteins. Mice deficient for Atg5 (autophagy-related 5) specifically in neural cells develop progressive deficits in motor function that are accompanied by the accumulation of cytoplasmic inclusion bodies in neurons. In Atg5-/- cells, diffuse, abnormal intracellular proteins accumulate, and then form aggregates and inclusions. These results suggest that the continuous clearance of diffuse cytosolic proteins through basal autophagy is important for preventing the accumulation of abnormal proteins, which can disrupt neural function and ultimately lead to neurodegeneration.
Comment in
- Neurodegeneration: good riddance to bad rubbish.
Klionsky DJ. Klionsky DJ. Nature. 2006 Jun 15;441(7095):819-20. doi: 10.1038/441819a. Nature. 2006. PMID: 16778876 No abstract available. - The importance of 'self-eating'.
Wrighton KH. Wrighton KH. Nat Rev Mol Cell Biol. 2010 Oct;11(10):681. doi: 10.1038/nrm2978. Nat Rev Mol Cell Biol. 2010. PMID: 20861878 No abstract available.
Similar articles
- Loss of autophagy in the central nervous system causes neurodegeneration in mice.
Komatsu M, Waguri S, Chiba T, Murata S, Iwata J, Tanida I, Ueno T, Koike M, Uchiyama Y, Kominami E, Tanaka K. Komatsu M, et al. Nature. 2006 Jun 15;441(7095):880-4. doi: 10.1038/nature04723. Epub 2006 Apr 19. Nature. 2006. PMID: 16625205 - Intracellular quality control by autophagy: how does autophagy prevent neurodegeneration?
Mizushima N, Hara T. Mizushima N, et al. Autophagy. 2006 Oct-Dec;2(4):302-4. doi: 10.4161/auto.2945. Epub 2006 Oct 25. Autophagy. 2006. PMID: 16874082 - Neurodegeneration: good riddance to bad rubbish.
Klionsky DJ. Klionsky DJ. Nature. 2006 Jun 15;441(7095):819-20. doi: 10.1038/441819a. Nature. 2006. PMID: 16778876 No abstract available. - Inclusion body formation, macroautophagy, and the role of HDAC6 in neurodegeneration.
Richter-Landsberg C, Leyk J. Richter-Landsberg C, et al. Acta Neuropathol. 2013 Dec;126(6):793-807. doi: 10.1007/s00401-013-1158-x. Epub 2013 Aug 3. Acta Neuropathol. 2013. PMID: 23912309 Review. - Dining in with BCL-2: new guests at the autophagy table.
Germain M, Slack RS. Germain M, et al. Clin Sci (Lond). 2009 Oct 26;118(3):173-81. doi: 10.1042/CS20090310. Clin Sci (Lond). 2009. PMID: 19845510 Review.
Cited by
- Autophagy-lysosomal pathway impairment and cathepsin dysregulation in Alzheimer's disease.
Mançano ASF, Pina JG, Froes BR, Sciani JM. Mançano ASF, et al. Front Mol Biosci. 2024 Oct 31;11:1490275. doi: 10.3389/fmolb.2024.1490275. eCollection 2024. Front Mol Biosci. 2024. PMID: 39544403 Free PMC article. Review. - STING orchestrates microglia polarization via interaction with LC3 in autophagy after ischemia.
Kong L, Xu P, Shen N, Li W, Li R, Tao C, Wang G, Zhang Y, Sun W, Hu W, Liu X. Kong L, et al. Cell Death Dis. 2024 Nov 13;15(11):824. doi: 10.1038/s41419-024-07208-1. Cell Death Dis. 2024. PMID: 39537618 Free PMC article. - Epidermal maintenance of Langerhans cells relies on autophagy-regulated lipid metabolism.
Arbogast F, Sal-Carro R, Boufenghour W, Frenger Q, Bouis D, Filippi De La Palavesa L, Fauny JD, Griso O, Puccio H, Fima R, Huby T, Gautier EL, Molitor A, Carapito R, Bahram S, Romani N, Clausen BE, Voisin B, Mueller CG, Gros F, Flacher V. Arbogast F, et al. J Cell Biol. 2025 Feb 3;224(2):e202403178. doi: 10.1083/jcb.202403178. Epub 2024 Nov 13. J Cell Biol. 2025. PMID: 39535446 Free PMC article. - The role of autophagy in brain health and disease: Insights into exosome and autophagy interactions.
Wang HD, Lv CL, Feng L, Guo JX, Zhao SY, Jiang P. Wang HD, et al. Heliyon. 2024 Oct 4;10(21):e38959. doi: 10.1016/j.heliyon.2024.e38959. eCollection 2024 Nov 15. Heliyon. 2024. PMID: 39524893 Free PMC article. Review. - Lysosomal physiology and pancreatic lysosomal stress in diabetes mellitus.
Hao M, Sebag SC, Qian Q, Yang L. Hao M, et al. eGastroenterology. 2024 Oct;2(3):e100096. doi: 10.1136/egastro-2024-100096. Epub 2024 Aug 29. eGastroenterology. 2024. PMID: 39512752 Free PMC article.
Publication types
MeSH terms
Substances
LinkOut - more resources
Full Text Sources
Other Literature Sources
Medical
Molecular Biology Databases