Lymphocytes are dispensable for glomerulonephritis but required for renal interstitial fibrosis in matrix defect-induced Alport renal disease - PubMed (original) (raw)
Lymphocytes are dispensable for glomerulonephritis but required for renal interstitial fibrosis in matrix defect-induced Alport renal disease
Valerie S Lebleu et al. Lab Invest. 2008 Mar.
Free article
Abstract
One current theory for the emergence of glomerular nephritis implicates Th1-type cellular responses associated with delayed-type hypersensitivity, involving T cells and macrophages. Using a mouse model for progressive glomerulonephritis, we investigate the role of B and T cells in the pathogenesis of glomerular inflammation. Deletion of alpha3 chain of type IV collagen in mice (alpha3(IV) collagen null mice) results in GBM defects, glomerulonephritis and tubulointerstitial inflammation, fibrosis and significant immune infiltration including activated B- and T-lymphocytes. To evaluate the contribution of lymphocytes to the pathogenesis of glomerulonephritis and renal fibrosis, we generated mice that are deficient in both the alpha3(IV) collagen and Rag-1 (alpha3/Rag-1 DKO). Lymphocyte deficiency significantly reduces fibrosis in the renal interstitium, but ultrastructural GBM defects persist. Interestingly, glomerulonephritis in the double null mice persists at a similar level with comparable proteinuria. Here we demonstrate that despite the presence of B-cell and T-cells in the inflamed glomeruli, their deletion does not impede the emergence of glomerulonephritis but has a negative impact on the progression of renal interstitial fibrosis.
Similar articles
- Stage-specific action of matrix metalloproteinases influences progressive hereditary kidney disease.
Zeisberg M, Khurana M, Rao VH, Cosgrove D, Rougier JP, Werner MC, Shield CF 3rd, Werb Z, Kalluri R. Zeisberg M, et al. PLoS Med. 2006 Apr;3(4):e100. doi: 10.1371/journal.pmed.0030100. Epub 2006 Mar 7. PLoS Med. 2006. PMID: 16509766 Free PMC article. - Collagen receptors integrin alpha2beta1 and discoidin domain receptor 1 regulate maturation of the glomerular basement membrane and loss of integrin alpha2beta1 delays kidney fibrosis in COL4A3 knockout mice.
Rubel D, Frese J, Martin M, Leibnitz A, Girgert R, Miosge N, Eckes B, Müller GA, Gross O. Rubel D, et al. Matrix Biol. 2014 Feb;34:13-21. doi: 10.1016/j.matbio.2014.01.006. Epub 2014 Jan 27. Matrix Biol. 2014. PMID: 24480069 - Upregulated expression of integrin α1 in mesangial cells and integrin α3 and vimentin in podocytes of Col4a3-null (Alport) mice.
Steenhard BM, Vanacore R, Friedman D, Zelenchuk A, Stroganova L, Isom K, St John PL, Hudson BG, Abrahamson DR. Steenhard BM, et al. PLoS One. 2012;7(12):e50745. doi: 10.1371/journal.pone.0050745. Epub 2012 Dec 7. PLoS One. 2012. PMID: 23236390 Free PMC article. - Autoepitopes and alloepitopes of type IV collagen: role in the molecular pathogenesis of anti-GBM antibody glomerulonephritis.
Borza DB. Borza DB. Nephron Exp Nephrol. 2007;106(2):e37-43. doi: 10.1159/000101791. Epub 2007 Jun 6. Nephron Exp Nephrol. 2007. PMID: 17570938 Review. - Alport syndrome and thin glomerular basement membrane nephropathy: a practical approach to diagnosis.
Haas M. Haas M. Arch Pathol Lab Med. 2009 Feb;133(2):224-32. doi: 10.5858/133.2.224. Arch Pathol Lab Med. 2009. PMID: 19195966 Review.
Cited by
- Mefunidone attenuates tubulointerstitial fibrosis in a rat model of unilateral ureteral obstruction.
Liu C, Mei W, Tang J, Yuan Q, Huang L, Lu M, Wu L, Peng Z, Meng J, Yang H, Shen H, Lv B, Hu G, Tao L. Liu C, et al. PLoS One. 2015 Jun 4;10(6):e0129283. doi: 10.1371/journal.pone.0129283. eCollection 2015. PLoS One. 2015. PMID: 26042668 Free PMC article. - Progression of Alport Kidney Disease in Col4a3 Knock Out Mice Is Independent of Sex or Macrophage Depletion by Clodronate Treatment.
Kim M, Piaia A, Shenoy N, Kagan D, Gapp B, Kueng B, Weber D, Dietrich W, Ksiazek I. Kim M, et al. PLoS One. 2015 Nov 10;10(11):e0141231. doi: 10.1371/journal.pone.0141231. eCollection 2015. PLoS One. 2015. PMID: 26555339 Free PMC article. - Collagen IV diseases: A focus on the glomerular basement membrane in Alport syndrome.
Cosgrove D, Liu S. Cosgrove D, et al. Matrix Biol. 2017 Jan;57-58:45-54. doi: 10.1016/j.matbio.2016.08.005. Epub 2016 Aug 27. Matrix Biol. 2017. PMID: 27576055 Free PMC article. Review. - Inflammation in chronic kidney disease: role in the progression of renal and cardiovascular disease.
Silverstein DM. Silverstein DM. Pediatr Nephrol. 2009 Aug;24(8):1445-52. doi: 10.1007/s00467-008-1046-0. Epub 2008 Dec 13. Pediatr Nephrol. 2009. PMID: 19083024 Review. - Intravital imaging reveals glomerular capillary distension and endothelial and immune cell activation early in Alport syndrome.
Gyarmati G, Shroff UN, Izuhara A, Hou X, Da Sacco S, Sedrakyan S, Lemley KV, Amann K, Perin L, Peti-Peterdi J. Gyarmati G, et al. JCI Insight. 2022 Jan 11;7(1):e152676. doi: 10.1172/jci.insight.152676. JCI Insight. 2022. PMID: 34793332 Free PMC article.
Publication types
MeSH terms
Substances
LinkOut - more resources
Full Text Sources
Molecular Biology Databases