Telangiectases in scleroderma: a potential clinical marker of pulmonary arterial hypertension - PubMed (original) (raw)
Telangiectases in scleroderma: a potential clinical marker of pulmonary arterial hypertension
Ami A Shah et al. J Rheumatol. 2010 Jan.
Abstract
Objective: Clinical markers are needed to identify scleroderma patients at risk for pulmonary arterial hypertension (PAH) since early therapy may improve survival. We investigated whether increased numbers of telangiectases in scleroderma associate with measures of pulmonary vascular disease.
Methods: One hundred forty-seven consecutive adult patients with scleroderma were enrolled in this cross-sectional study and scored for the presence of matted telangiectases on 11 body areas. Per body area, telangiectases were scored as 0 if none were present, 1 if there were fewer than 10 telangiectases, and 2 if 10 or more telangiectases were counted. Linear regression analysis was performed to assess the association between right ventricular systolic pressure (RVSP) and telangiectasia score, adjusted for age, race, smoking status, scleroderma subtype, disease duration, and autoantibody status. Logistic regression analysis was performed with PAH by right-heart catheterization (RHC) as the dependent variable.
Results: The mean telangiectasia score was 6.0 (SD 4.5, range 0-20). RVSP and telangiectasia score were positively correlated (r = 0.271, p = 0.001). The mean RVSP increased by 10.9 mm Hg for every 10-point increase in telangiectasia score (95% CI 3.6-18.3 mm Hg, p = 0.004), adjusted for potential confounders. The adjusted relative odds of PAH by RHC were 12.4 for patients with a 10-point increase in telangiectasia score (95% CI 1.78-85.9, p = 0.01).
Conclusion: Increased numbers of telangiectases strongly associate with the presence of pulmonary vascular disease. Telangiectases may be a clinical marker of more widespread aberrant microvascular disease in scleroderma.
Figures
Figure 1
Two different types of telangiectasia: (A) matted; (B) stellate.
Figure 2
The mean telangiectasia score increased by 2.5 for every 10-year increase in scleroderma disease duration (p < 0.001).
Figure 3
The mean RVSP increased by 10.8 mm Hg for every 10-point increase in telangiectasia score (p = 0.001).
Figure 4
Total telangiectasia score by pulmonary arterial hypertension (PAH) status. PAH is defined as either an estimated right ventricular systolic pressure (RVSP) ≥ 45 mm Hg or right-heart catheterization–confirmed PAH.
Similar articles
- Exercise-induced pulmonary arterial hypertension in patients with systemic sclerosis.
Steen V, Chou M, Shanmugam V, Mathias M, Kuru T, Morrissey R. Steen V, et al. Chest. 2008 Jul;134(1):146-51. doi: 10.1378/chest.07-2324. Epub 2008 Apr 10. Chest. 2008. PMID: 18403670 Clinical Trial. - Age and risk of pulmonary arterial hypertension in scleroderma.
Schachna L, Wigley FM, Chang B, White B, Wise RA, Gelber AC. Schachna L, et al. Chest. 2003 Dec;124(6):2098-104. doi: 10.1378/chest.124.6.2098. Chest. 2003. PMID: 14665486 - Changes in estimated right ventricular systolic pressure predict mortality and pulmonary hypertension in a cohort of scleroderma patients.
Shah AA, Chung SE, Wigley FM, Wise RA, Hummers LK. Shah AA, et al. Ann Rheum Dis. 2013 Jul;72(7):1136-40. doi: 10.1136/annrheumdis-2012-201861. Epub 2012 Aug 11. Ann Rheum Dis. 2013. PMID: 22887850 Free PMC article. - Monitoring and Diagnostic Approaches for Pulmonary Arterial Hypertension in Patients with Systemic Sclerosis.
Valenzuela A, Nandagopal S, Steen VD, Chung L. Valenzuela A, et al. Rheum Dis Clin North Am. 2015 Aug;41(3):489-506. doi: 10.1016/j.rdc.2015.04.009. Epub 2015 May 20. Rheum Dis Clin North Am. 2015. PMID: 26210131 Review. - Pulmonary hypertension: a correct diagnosis for a suitable therapy in scleroderma patients.
Giordano N, Montella A, Corallo C, Ruocco G, Chirico C, Palazzuoli A, Nuti R, Pecetti G. Giordano N, et al. Clin Exp Rheumatol. 2015 Jul-Aug;33(4 Suppl 91):S182-9. Epub 2015 Sep 1. Clin Exp Rheumatol. 2015. PMID: 26339897 Review.
Cited by
- Can Combination Therapy with Endothelin Receptor Antagonist and PDE5 Inhibitors Prevent Echocardiographic Findings Suspicious for Pulmonary Arterial Hypertension? Description of a Real-Life Case Series.
Damiani A, Lepri G, Bonomi F, Fiorentini E, Peretti S, Blagojevic J, Bellando Randone S, Guiducci S. Damiani A, et al. Diagnostics (Basel). 2024 Jul 15;14(14):1526. doi: 10.3390/diagnostics14141526. Diagnostics (Basel). 2024. PMID: 39061663 Free PMC article. - The effectiveness and value of sotatercept for pulmonary arterial hypertension: A summary from the Institute for Clinical and Economic Review's Midwest Comparative Effectiveness Public Advisory Council.
Nikitin D, Lin GA, Whittington MD, Nhan E, Kayali Y, Rind DM, Pearson SD, Agboola F. Nikitin D, et al. J Manag Care Spec Pharm. 2024 May;30(5):491-495. doi: 10.18553/jmcp.2024.30.5.491. J Manag Care Spec Pharm. 2024. PMID: 38701024 Free PMC article. No abstract available. - Systemic sclerosis patients with negative antinuclear antibodies have distinctive clinical manifestations: a multicenter CRDC cohort in China.
Hui M, Wang X, Zhou J, Zhang L, Duan X, Li M, Wang Q, Zhao J, Hou Y, Xu D, Zeng X. Hui M, et al. Z Rheumatol. 2024 Feb;83(Suppl 1):160-166. doi: 10.1007/s00393-022-01242-0. Epub 2022 Jul 19. Z Rheumatol. 2024. PMID: 35852599 English. - Systemic Scleroderma-Definition, Clinical Picture and Laboratory Diagnostics.
Kowalska-Kępczyńska A. Kowalska-Kępczyńska A. J Clin Med. 2022 Apr 20;11(9):2299. doi: 10.3390/jcm11092299. J Clin Med. 2022. PMID: 35566425 Free PMC article. Review. - Patient-reported outcome instruments in clinical trials of systemic sclerosis.
Pauling JD, Caetano J, Campochiaro C, De Luca G, Gheorghiu AM, Lazzaroni MG, Khanna D. Pauling JD, et al. J Scleroderma Relat Disord. 2020 Jun;5(2):90-102. doi: 10.1177/2397198319886496. Epub 2019 Nov 25. J Scleroderma Relat Disord. 2020. PMID: 35382020 Free PMC article. Review.
References
- Braverman IM, Ken-Yen A. Ultrastructure and three-dimensional reconstruction of several macular and papular telangiectases. J Invest Dermatol. 1983;81:489–497. - PubMed
- Walker JG, Stirling J, Beroukas D, Dharmapatni K, Haynes DR, Smith MD, et al. Histopathological and ultrastructural features of dermal telangiectasias in systemic sclerosis. Pathology. 2005;37:220–225. - PubMed
- Wigley FM. Vascular disease in scleroderma. Clin Rev Allergy Immunol. 2009;36:150–175. - PubMed
- Preliminary criteria for the classification of systemic sclerosis (scleroderma). Subcommittee for scleroderma criteria of the American Rheumatism Association Diagnostic and Therapeutic Criteria Committee. Arthritis Rheum. 1980;23:581–590. - PubMed
- LeRoy EC, Black C, Fleischmajer R, Jablonska S, Krieg T, Medsger TA, Jr, et al. Scleroderma (systemic sclerosis): classification, subsets and pathogenesis. J Rheumatol. 1988;15:202–205. - PubMed
Publication types
MeSH terms
Substances
Grants and funding
- 1K23AR052742/AR/NIAMS NIH HHS/United States
- P50 HL084946/HL/NHLBI NIH HHS/United States
- T32 AR048522/AR/NIAMS NIH HHS/United States
- K23 AR052742/AR/NIAMS NIH HHS/United States
- 1P50 HL084946-01/HL/NHLBI NIH HHS/United States
LinkOut - more resources
Full Text Sources
Medical