Associated autoimmune diseases in patients with multifocal motor neuropathy and their family members - PubMed (original) (raw)
Associated autoimmune diseases in patients with multifocal motor neuropathy and their family members
Elisabeth A Cats et al. J Neurol. 2012 Jun.
Abstract
Multifocal motor neuropathy (MMN) is a rare immune-mediated disorder and is characterized by male predominance, the presence of serum anti-GM1 IgM antibodies in up to half of all patients, responsiveness to intravenous immunoglobulins (IVIg) and an increased frequency of HLA type HLA-DRB1*15. The aim of this study was to assess whether the frequency of autoimmune diseases (AID) is increased in patients with MMN and their first-degree family members, since this would indicate that MMN shares pathogenic mechanisms with other AID. We conducted a case-control study using questionnaires to evaluate the prevalence of AID in MMN and controls, and their first-degree relatives. Questionnaires from 81 MMN patients (417 first-degree relatives) and 438 controls (2,377 first-degree relatives) were analyzed. Overall prevalence of AID was higher in MMN patients (11%) than in controls (5%) (OR 2.4, 95% CI 1.1-5.5, p = 0.037). Type 1 diabetes, Hashimoto's thyroid disease, and celiac disease were significantly more prevalent in family members of patients than controls. The presence of an additional AID was not associated with age at MMN onset, disease duration, titer of serum anti-GM1 IgM antibodies or HLA type HLA-DRB1*15. The higher frequency of AID in patients with MMN indicates a common autoimmune diathesis.
Similar articles
- Immune pathogenesis and treatment of multifocal motor neuropathy.
Vlam L, van den Berg LH, Cats EA, Piepers S, van der Pol WL. Vlam L, et al. J Clin Immunol. 2013 Jan;33 Suppl 1:S38-42. doi: 10.1007/s10875-012-9779-8. Epub 2012 Sep 2. J Clin Immunol. 2013. PMID: 22941513 Review. - IgM anti-GM2 antibodies in patients with multifocal motor neuropathy target Schwann cells and are associated with early onset.
Budding K, Bos JW, Dijkxhoorn K, de Zeeuw E, Bloemenkamp LM, Zekveld EM, Groen EJN, Jacobs BC, Huizinga R, Goedee HS, Cats EA, Leusen JHW, van den Berg LH, Hack CE, van der Pol WL. Budding K, et al. J Neuroinflammation. 2024 Apr 17;21(1):100. doi: 10.1186/s12974-024-03090-y. J Neuroinflammation. 2024. PMID: 38632654 Free PMC article. - Sensitivity and predictive value of anti-GM1/galactocerebroside IgM antibodies in multifocal motor neuropathy.
Nobile-Orazio E, Giannotta C, Musset L, Messina P, Léger JM. Nobile-Orazio E, et al. J Neurol Neurosurg Psychiatry. 2014 Jul;85(7):754-8. doi: 10.1136/jnnp-2013-305755. Epub 2013 Aug 1. J Neurol Neurosurg Psychiatry. 2014. PMID: 23907602 - Childhood-onset multifocal motor neuropathy with IgM antibodies to GM2 and GalNac-GD1a.
Maeda H, Ishii R, Kusunoki S, Chiyonobu T. Maeda H, et al. Brain Dev. 2020 Jan;42(1):88-92. doi: 10.1016/j.braindev.2019.08.013. Epub 2019 Sep 12. Brain Dev. 2020. PMID: 31522790 - Multifocal motor neuropathy.
Beadon K, Guimarães-Costa R, Léger JM. Beadon K, et al. Curr Opin Neurol. 2018 Oct;31(5):559-564. doi: 10.1097/WCO.0000000000000605. Curr Opin Neurol. 2018. PMID: 30102608 Review.
Cited by
- MMN: from immunological cross-talk to conduction block.
Harschnitz O, Jongbloed BA, Franssen H, Straver DC, van der Pol WL, van den Berg LH. Harschnitz O, et al. J Clin Immunol. 2014 Jul;34 Suppl 1(Suppl 1):S112-9. doi: 10.1007/s10875-014-0026-3. Epub 2014 Apr 13. J Clin Immunol. 2014. PMID: 24728842 Free PMC article. Review. - The pathogenesis of multifocal motor neuropathy and an update on current management options.
Léger JM, Guimarães-Costa R, Iancu Ferfoglia R. Léger JM, et al. Ther Adv Neurol Disord. 2015 May;8(3):109-22. doi: 10.1177/1756285615575269. Ther Adv Neurol Disord. 2015. PMID: 25941538 Free PMC article. Review. - Autoimmune disease preceding amyotrophic lateral sclerosis: an epidemiologic study.
Turner MR, Goldacre R, Ramagopalan S, Talbot K, Goldacre MJ. Turner MR, et al. Neurology. 2013 Oct 1;81(14):1222-5. doi: 10.1212/WNL.0b013e3182a6cc13. Epub 2013 Aug 14. Neurology. 2013. PMID: 23946298 Free PMC article. - Multifocal motor neuropathy: a review of pathogenesis, diagnosis, and treatment.
Lawson VH, Arnold WD. Lawson VH, et al. Neuropsychiatr Dis Treat. 2014 Apr 5;10:567-76. doi: 10.2147/NDT.S39592. eCollection 2014. Neuropsychiatr Dis Treat. 2014. PMID: 24741315 Free PMC article. Review. - Immune pathogenesis and treatment of multifocal motor neuropathy.
Vlam L, van den Berg LH, Cats EA, Piepers S, van der Pol WL. Vlam L, et al. J Clin Immunol. 2013 Jan;33 Suppl 1:S38-42. doi: 10.1007/s10875-012-9779-8. Epub 2012 Sep 2. J Clin Immunol. 2013. PMID: 22941513 Review.
References
- Briani C, Zara G, Toffanin E, Ruggero S, Ferrarini A, De LF, Luca M, Faggian D, Grassivaro F, Ermani M, Pezzani R, Giometto B, D’Odorico A. Neurological complications of celiac disease and autoimmune mechanisms: preliminary data of a prospective study in adult patients. Ann NY Acad Sci. 2005;1051:148–155. doi: 10.1196/annals.1361.056. - DOI - PubMed
MeSH terms
LinkOut - more resources
Full Text Sources
Medical
Research Materials