Genetic interaction between hoxb-5 and hoxb-6 is revealed by nonallelic noncomplementation - PubMed (original) (raw)
. 1995 Jan 1;9(1):108-22.
doi: 10.1101/gad.9.1.108.
Affiliations
- PMID: 7828847
- DOI: 10.1101/gad.9.1.108
Free article
Genetic interaction between hoxb-5 and hoxb-6 is revealed by nonallelic noncomplementation
D E Rancourt et al. Genes Dev. 1995.
Free article
Abstract
hoxb-5 and hoxb-6 are adjacent genes in the mouse HoxB locus and are members of the homeotic transcription factor complex that governs establishment of the mammalian body plan. To determine the roles of these genes during development, we generated mice with a targeted disruption in each gene. Three phenotypes affecting brachiocervicothoracic structures were found in the mutant mice. First, hoxb-5- homozygotes have a rostral shift of the shoulder girdle, analogous to what is seen in the human Sprengel anomaly. This suggests a role for hoxb-5 in specifying the position of limbs along the anteroposterior axis of the vertebrate body. Second, hoxb-6- homozygotes frequently have a missing first rib and a bifid second rib. The third phenotype, an anteriorizing homeotic transformation of the cervicothoracic vertebrae from C6 through T1, is common to both hoxb-5- and hoxb-6- homozygotes. Quite unexpectedly, hoxb-5, hoxb-6 transheterozygotes (hoxb-5-hoxb-6+/hoxb-5+ hoxb-6-) also show the third phenotype. By this classical genetic complementation test, these two mutations appear as alleles of the same gene. This phenomenon is termed nonallelic noncomplementation and suggests that these two genes function together to specify this region of the mammalian vertebral column.
Similar articles
- Mutations in paralogous Hox genes result in overlapping homeotic transformations of the axial skeleton: evidence for unique and redundant function.
Horan GS, Kovàcs EN, Behringer RR, Featherstone MS. Horan GS, et al. Dev Biol. 1995 May;169(1):359-72. doi: 10.1006/dbio.1995.1150. Dev Biol. 1995. PMID: 7750651 - Targeted disruption of the Hoxb-2 locus in mice interferes with expression of Hoxb-1 and Hoxb-4.
Barrow JR, Capecchi MR. Barrow JR, et al. Development. 1996 Dec;122(12):3817-28. doi: 10.1242/dev.122.12.3817. Development. 1996. PMID: 9012503 - Compound mutants for the paralogous hoxa-4, hoxb-4, and hoxd-4 genes show more complete homeotic transformations and a dose-dependent increase in the number of vertebrae transformed.
Horan GS, Ramírez-Solis R, Featherstone MS, Wolgemuth DJ, Bradley A, Behringer RR. Horan GS, et al. Genes Dev. 1995 Jul 1;9(13):1667-77. doi: 10.1101/gad.9.13.1667. Genes Dev. 1995. PMID: 7628700 - Developmental anomalies of the scapula-the "omo"st forgotten bone.
Williams MS. Williams MS. Am J Med Genet A. 2003 Aug 1;120A(4):583-7. doi: 10.1002/ajmg.a.20091. Am J Med Genet A. 2003. PMID: 12884444 Review. - Sometimes the result is not the answer: the truths and the lies that come from using the complementation test.
Hawley RS, Gilliland WD. Hawley RS, et al. Genetics. 2006 Sep;174(1):5-15. doi: 10.1534/genetics.106.064550. Genetics. 2006. PMID: 16988106 Free PMC article. Review.
Cited by
- Longevity genes in the nematode Caenorhabditis elegans also mediate increased resistance to stress and prevent disease.
Johnson TE, Henderson S, Murakami S, de Castro E, de Castro SH, Cypser J, Rikke B, Tedesco P, Link C. Johnson TE, et al. J Inherit Metab Dis. 2002 May;25(3):197-206. doi: 10.1023/a:1015677828407. J Inherit Metab Dis. 2002. PMID: 12137228 Review. - Genetic knockouts in mice: an update.
Shastry BS. Shastry BS. Experientia. 1995 Nov 15;51(11):1028-39. doi: 10.1007/BF01946911. Experientia. 1995. PMID: 7498440 Review. - Hox5 interacts with Plzf to restrict Shh expression in the developing forelimb.
Xu B, Hrycaj SM, McIntyre DC, Baker NC, Takeuchi JK, Jeannotte L, Gaber ZB, Novitch BG, Wellik DM. Xu B, et al. Proc Natl Acad Sci U S A. 2013 Nov 26;110(48):19438-43. doi: 10.1073/pnas.1315075110. Epub 2013 Nov 11. Proc Natl Acad Sci U S A. 2013. PMID: 24218595 Free PMC article. - Unique spatial and cellular expression patterns of Hoxa5, Hoxb4, and Hoxb6 proteins in normal developing murine lung are modified in pulmonary hypoplasia.
Volpe MV, Wang KT, Nielsen HC, Chinoy MR. Volpe MV, et al. Birth Defects Res A Clin Mol Teratol. 2008 Aug;82(8):571-84. doi: 10.1002/bdra.20481. Birth Defects Res A Clin Mol Teratol. 2008. PMID: 18553509 Free PMC article. - Enrichment and efficient screening of ES cells containing a targeted mutation: the use of DT-A gene with the polyadenylation signal as a negative selection maker.
Yanagawa Y, Kobayashi T, Ohnishi M, Kobayashi T, Tamura S, Tsuzuki T, Sanbo M, Yagi T, Tashiro F, Miyazaki J. Yanagawa Y, et al. Transgenic Res. 1999 Jun;8(3):215-21. doi: 10.1023/a:1008914020843. Transgenic Res. 1999. PMID: 10478491
Publication types
MeSH terms
Substances
LinkOut - more resources
Full Text Sources
Other Literature Sources
Molecular Biology Databases