Diagnosis of Creutzfeldt-Jakob disease by measurement of S100 protein in serum: prospective case-control study - PubMed (original) (raw)
. 1998 Feb 21;316(7131):577-82.
doi: 10.1136/bmj.316.7131.577.
J Wiltfang, E Schütz, I Zerr, A Otto, A Pfahlberg, O Gefeller, M Uhr, A Giese, T Weber, H A Kretzschmar, S Poser
Affiliations
- PMID: 9518907
- PMCID: PMC28459
- DOI: 10.1136/bmj.316.7131.577
Diagnosis of Creutzfeldt-Jakob disease by measurement of S100 protein in serum: prospective case-control study
M Otto et al. BMJ. 1998.
Erratum in
- BMJ 1998 Jul 18;317(7152):177
Abstract
Objective: To analyse serum concentrations of brain specific S100 protein in patients with Creutzfeldt-Jakob disease and in controls.
Design: Prospective case-control study.
Setting: National Creutzfeldt-Jakob disease surveillance unit.
Subjects: 224 patients referred to the surveillance unit with suspected Creutzfeldt-Jakob disease and 35 control patients without dementia.
Main outcome measure: Serum concentration of S100 protein in patients with Creutzfeldt-Jakob disease, in patients with other diseases causing dementia, and in the control group.
Results: Of the 224 patients with suspected Creutzfeldt-Jakob disease, 65 were classed as definitely having the disease after neuropathological verification, an additional 6 were classed as definitely having the disease as a result of a genetic mutation, 43 as probably having the disease, 36 as possibly having the disease, and 74 patients were classed as having other disease. In the 108 patients classed as definitely or probably having Creutzfeldt-Jakob disease the median serum concentration of S100 was 395 pg/ml (SD 387 pg/ml). This was significantly higher than concentrations found in the 74 patients classed as having other diseases (median 109 pg/ml; SD 177 pg/ml; P = 0.0001). At a cut off point of 213 pg/ml sensitivity for the diagnosis of the disease was 77.8% (95% confidence interval 68.8% to 85.2%) and specificity was 81.1% (70.3% to 89.3%). There was a significant difference in survival at different concentrations of S100 in Kaplan-Meier curves (P = 0.023).
Conclusion: Measurement of serum concentrations of S100 is a valuable tool which can be used more easily than tests on cerebrospinal fluid in the differential diagnosis of Creutzfeldt-Jakob disease. More studies are needed to determine whether serial testing of serum S100 improves diagnostic accuracy.
Figures
Figure 1
Serum concentrations of S100 protein by final diagnosis. 10th, 25th, 75th, and 90th percentiles are shown. CJD=Creutzfeldt-Jakob disease; *Patient with meningoencephalitis; †Patient with amyotrophic lateral sclerosis
Figure 2
Curve of receiver operating characteristics at different cut off points of serum concentration of S100 protein
Figure 3
Kaplan-Meier survival curves at different serum concentrations of S100 protein (P=0.023)
Comment in
- Early identification of variant Creutzfeldt-Jakob disease.
Pocchiari M. Pocchiari M. BMJ. 1998 Feb 21;316(7131):563-4. doi: 10.1136/bmj.316.7131.563. BMJ. 1998. PMID: 9518890 Free PMC article. No abstract available. - Diagnosis of Creutzfeldt-Jakob disease by measurement of S100 protein in serum. Appropriate study populations must be used.
McConville JP, Craig JJ. McConville JP, et al. BMJ. 1998 Aug 15;317(7156):472; author reply 472-3. BMJ. 1998. PMID: 9703539 Free PMC article. No abstract available. - Diagnosis of Creutzfeldt-Jakob disease by measurement of S100 protein in serum. Tonsil biopsy helps diagnose new variant Creutzfeldt-Jakob disease.
Collinge J, Rossor MN, Thomas D, Frosh A, Tolley N. Collinge J, et al. BMJ. 1998 Aug 15;317(7156):472-3. BMJ. 1998. PMID: 9758471 No abstract available. - Diagnosis of Creutzfeldt-Jakob disease. Subtypes of S100 proteins must be identified.
Heizmann CW. Heizmann CW. BMJ. 1999 Feb 20;318(7182):538. BMJ. 1999. PMID: 10223794 No abstract available.
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