Genome-Engineering Tools to Establish Accurate Reporter Cell Lines That Enable Identification of Therapeutic Strategies to Treat Friedreich's Ataxia (original) (raw)

Limitations in a frataxin knockdown cell model for Friedreich ataxia in a high-throughput drug screen

H. Seznec

BMC Neurology, 2009

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Activation of Frataxin Protein Expression by Antisense Oligonucleotides Targeting the Mutant Expanded Repeat

Vivek Sharma

Nucleic acid therapeutics, 2018

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Adding a temporal dimension to the study of Friedreich's ataxia: the effect of frataxin overexpression in a human cell model

Luca Quaroni

Disease models & mechanisms, 2018

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The First Cellular Models Based on Frataxin Missense Mutations That Reproduce Spontaneously the Defects Associated with Friedreich Ataxia

Marie Wattenhofer-Donzé

PLoS ONE, 2009

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Selection of Synthetic Proteins to Modulate the Human Frataxin Function

Martin Aran

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Increasing frataxin gene expression with histone deacetylase inhibitors as a therapeutic approach for Friedreich's ataxia

Joel Gottesfeld

Journal of Neurochemistry, 2013

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An AAV9 coding for frataxin clearly improved the symptoms and prolonged the life of Friedreich ataxia mouse models

Mohammed Filali

Molecular Therapy — Methods & Clinical Development, 2014

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Functional recovery in a Friedreich's ataxia mouse model by frataxin gene transfer using an HSV-1 amplicon vector

Javier Diaz-Nido

Molecular …, 2007

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Cell and Gene Therapy for Friedreich Ataxia: Progress to Date

Marguerite Evans-Galea

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Deletion of the GAA repeats from the human frataxin gene using the CRISPR-Cas9 system in YG8R-derived cells and mouse models of Friedreich ataxia

khadija Cherif

Gene Therapy, 2016

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Functional genomic analysis of frataxin deficiency reveals tissue-specific alterations and identifies the PPAR pathway as a therapeutic target in Friedreich's ataxia

Giovanni Coppola

Human Molecular Genetics, 2009

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Beyond Loss of Frataxin: the Complex Molecular Pathology of Friedreich Ataxia

Marguerite Evans-Galea

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Frataxin-deficient neurons and mice models of Friedreich ataxia are improved by TAT-MTScs-FXN treatment

elena britti

Journal of cellular and molecular medicine, 2017

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Neurobehavioral deficits of mice expressing a low level of G127V mutant frataxin

Aamir Zuberi

Neurobiology of Disease

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Preventing the ubiquitin-proteasome-dependent degradation of frataxin, the protein defective in Friedreich's ataxia

Natascia Ventura

Human Molecular Genetics, 2011

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High levels of frataxin overexpression leads to mitochondrial and cardiac toxicity in mouse models

Laurent Monassier

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Increased Frataxin Expression Induced in Friedreich Ataxia Cells by Platinum TALE-VP64s or Platinum TALE-SunTag

khadija Cherif

Molecular Therapy - Nucleic Acids, 2018

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Gene expression profiling in frataxin deficient mice: Microarray evidence for significant expression changes without detectable neurodegeneration

Giovanni Coppola

Neurobiology of Disease, 2006

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HDAC Inhibitors Correct Frataxin Deficiency in a Friedreich Ataxia Mouse Model

Kiki April

PLOS One, 2008

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Functional genomic analysis of frataxin deficiency reveals tissue-specific alterations and identifies the PPARγ pathway as a therapeutic target in Friedreich's ataxia

Sergio Cocozza

Human molecular …, 2009

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Friedreich Ataxia: From GAA Triplet–Repeat Expansion to Frataxin Deficiency

Pragna Patel

The American Journal of Human Genetics, 2001

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Biophysical characterisation of the recombinant human frataxin precursor

Alejandro Ferrari

FEBS open bio, 2018

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Reduction in frataxin causes progressive accumulation of mitochondrial damage

Grazia Isaya

Human Molecular Genetics, 2003

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Exenatide induces frataxin expression and improves mitochondrial function in Friedreich ataxia

Jean-christophe Jonas

JCI Insight

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Synthesis of frataxin genes by direct assembly of serial deoxyoligonucleotide primers and its expression in Escherichia coli

Young Geol Yoon

Biotechnology and Bioprocess Engineering, 2013

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A new cellular model to follow Friedreich's ataxia development in a time-resolved way

Salvatore Adinolfi

Disease Models & Mechanisms, 2015

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Infectious delivery and expression of a 135 kb human FRDA genomic DNA locus complements Friedreich's ataxia deficiency in human cells

Javier Diaz-Nido

Molecular …, 2007

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Reduction of Caenorhabditis elegans frataxin increases sensitivity to oxidative stress, reduces lifespan, and causes lethality in a mitochondrial complex II mutant

Pilar Cabo

The FASEB Journal, 2005

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Frataxin Silencing Inactivates Mitochondrial Complex I in NSC34 Motoneuronal Cells and Alters Glutathione Homeostasis

Anna Pastore

International Journal of Molecular Sciences, 2014

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