The relationship of spinal muscular atrophy to motor neuron disease: investigation of SMN and NAIP gene deletions in sporadic and familial ALS - PubMed (original) (raw)
Comparative Study
The relationship of spinal muscular atrophy to motor neuron disease: investigation of SMN and NAIP gene deletions in sporadic and familial ALS
R W Orrell et al. J Neurol Sci. 1997 Jan.
Abstract
Amyotrophic lateral sclerosis (ALS) is found in a familial form in around 5-10% of cases. Of these familial cases around 20% are associated with mutations of SOD-1. The genetic basis of the disease in the remaining familial cases, and genetic risk factors in sporadic cases, are unknown. Recently, the common forms of spinal muscular atrophy (SMA) have been associated with mutations of the SMN and NAIP genes on chromosome 5, in the region q11.2-13.3. Some patients with both familial and sporadic motor neuron disease show only lower motor neuron signs, in common with SMA patients, and families containing individuals with phenotypes of both childhood SMA and adult motor neuron disease have been reported. We therefore examined the SMA locus as a candidate for ALS, in 54 patients with sporadic motor neuron disease, and 10 single-generation familial patients (with no evidence of SOD-1 mutations), and in a single patient with Brown-Vialetto-Van Laere syndrome. No mutations of the SMN or NAIP genes were detected. The difficulties of classification of lower motor neuron presentations of motor neuron diseases are discussed. The demonstration that mutations diagnostic of SMA are not found in ALS patients helps distinguish these conditions.
Similar articles
- Deletions causing spinal muscular atrophy do not predispose to amyotrophic lateral sclerosis.
Parboosingh JS, Meininger V, McKenna-Yasek D, Brown RH Jr, Rouleau GA. Parboosingh JS, et al. Arch Neurol. 1999 Jun;56(6):710-2. doi: 10.1001/archneur.56.6.710. Arch Neurol. 1999. PMID: 10369311 - Analysis of chromosome 5q13 genes in amyotrophic lateral sclerosis: homozygous NAIP deletion in a sporadic case.
Jackson M, Morrison KE, Al-Chalabi A, Bakker M, Leigh PN. Jackson M, et al. Ann Neurol. 1996 Jun;39(6):796-800. doi: 10.1002/ana.410390616. Ann Neurol. 1996. PMID: 8651652 - Molecular analysis of candidate genes on chromosome 5q13 in autosomal recessive spinal muscular atrophy: evidence of homozygous deletions of the SMN gene in unaffected individuals.
Hahnen E, Forkert R, Marke C, Rudnik-Schöneborn S, Schönling J, Zerres K, Wirth B. Hahnen E, et al. Hum Mol Genet. 1995 Oct;4(10):1927-33. doi: 10.1093/hmg/4.10.1927. Hum Mol Genet. 1995. PMID: 8595417 - Pathogenic commonalities between spinal muscular atrophy and amyotrophic lateral sclerosis: Converging roads to therapeutic development.
Bowerman M, Murray LM, Scamps F, Schneider BL, Kothary R, Raoul C. Bowerman M, et al. Eur J Med Genet. 2018 Nov;61(11):685-698. doi: 10.1016/j.ejmg.2017.12.001. Epub 2017 Dec 5. Eur J Med Genet. 2018. PMID: 29313812 Review. - Spinal muscular atrophies: recent insights and impact on molecular diagnosis.
Brahe C, Bertini E. Brahe C, et al. J Mol Med (Berl). 1996 Oct;74(10):555-62. doi: 10.1007/s001090050059. J Mol Med (Berl). 1996. PMID: 8912176 Review.
Cited by
- Long non-coding and coding RNAs characterization in Peripheral Blood Mononuclear Cells and Spinal Cord from Amyotrophic Lateral Sclerosis patients.
Gagliardi S, Zucca S, Pandini C, Diamanti L, Bordoni M, Sproviero D, Arigoni M, Olivero M, Pansarasa O, Ceroni M, Calogero R, Cereda C. Gagliardi S, et al. Sci Rep. 2018 Feb 5;8(1):2378. doi: 10.1038/s41598-018-20679-5. Sci Rep. 2018. PMID: 29402919 Free PMC article. - Copy Number Variations in the Survival Motor Neuron Genes: Implications for Spinal Muscular Atrophy and Other Neurodegenerative Diseases.
Butchbach ME. Butchbach ME. Front Mol Biosci. 2016 Mar 10;3:7. doi: 10.3389/fmolb.2016.00007. eCollection 2016. Front Mol Biosci. 2016. PMID: 27014701 Free PMC article. Review. - Brown-Vialetto-Van Laere syndrome.
Sathasivam S. Sathasivam S. Orphanet J Rare Dis. 2008 Apr 17;3:9. doi: 10.1186/1750-1172-3-9. Orphanet J Rare Dis. 2008. PMID: 18416855 Free PMC article. Review. - Molecular and cellular pathways of neurodegeneration in motor neurone disease.
Shaw PJ. Shaw PJ. J Neurol Neurosurg Psychiatry. 2005 Aug;76(8):1046-57. doi: 10.1136/jnnp.2004.048652. J Neurol Neurosurg Psychiatry. 2005. PMID: 16024877 Free PMC article. Review. - A novel locus for familial amyotrophic lateral sclerosis, on chromosome 18q.
Hand CK, Khoris J, Salachas F, Gros-Louis F, Lopes AA, Mayeux-Portas V, Brewer CG, Brown RH Jr, Meininger V, Camu W, Rouleau GA. Hand CK, et al. Am J Hum Genet. 2002 Jan;70(1):251-6. doi: 10.1086/337945. Epub 2001 Nov 9. Am J Hum Genet. 2002. PMID: 11706389 Free PMC article.
Publication types
MeSH terms
Substances
LinkOut - more resources
Full Text Sources
Medical
Miscellaneous